Professional Documents
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Review
A systematic review and classification of interventions for speech-sound
disorder in preschool children
Yvonne Wren†‡, Sam Harding†, Juliet Goldbart§ and Sue Roulstone†¶
†Bristol Speech and Language Therapy Research Unit, North Bristol NHS Trust, Bristol, UK
‡Faculty of Health Sciences, University of Bristol, UK
§Faculty of Health, Psychology and Social Care, Manchester Metropolitan University, UK
¶Faculty of Health and Applied Sciences, University of the West of England, Bristol, UK
(Received May 2017; accepted December 2017)
Abstract
Background: Multiple interventions have been developed to address speech sound disorder (SSD) in children.
Many of these have been evaluated but the evidence for these has not been considered within a model which
categorizes types of intervention. The opportunity to carry out a systematic review of interventions for SSD arose
as part of a larger scale study of interventions for primary speech and language impairment in preschool children.
Aims: To review systematically the evidence for interventions for SSD in preschool children and to categorize them
within a classification of interventions for SSD.
Methods & Procedures: Relevant search terms were used to identify intervention studies published up to 2012, with
the following inclusion criteria: participants were aged between 2 years and 5 years, 11 months; they exhibited
speech, language and communication needs; and a primary outcome measure of speech was used. Studies that
met inclusion criteria were quality appraised using the single case experimental design (SCED) or PEDro-P,
depending on their methodology. Those judged to be high quality were classified according to the primary focus
of intervention.
Outcomes & Results: The final review included 26 studies. Case series was the most common research design.
Categorization to the classification system for interventions showed that cognitive–linguistic and production
approaches to intervention were the most frequently reported. The highest graded evidence was for three studies
within the auditory–perceptual and integrated categories.
Conclusions & Implications: The evidence for intervention for preschool children with SSD is focused on seven out
of 11 subcategories of interventions. Although all the studies included in the review were good quality as defined
by quality appraisal checklists, they mostly represented lower-graded evidence. Higher-graded studies are needed
to understand clearly the strength of evidence for different interventions.
Address correspondence to: Yvonne Wren, Bristol Speech and Language Therapy Research Unit, Pines and Steps, Southmead Hospital,
Westbury-on-Trym, Bristol BS10 5NB, UK; e-mail: Yvonne.wren@bristol.ac.uk
International Journal of Language & Communication Disorders
ISSN 1368-2822 print/ISSN 1460-6984 online C 2018 Royal College of Speech and Language Therapists
DOI: 10.1111/1460-6984.12371
Systematic review of speech interventions 447
Figure 1. Model of intervention procedures for targeting speech-sound disorder (SSD). [Colour figure can be viewed at wileyonlinelibrary.com]
criteria within the model of classifications of interven- to the study methodologies, and built on the review un-
tions for SSD described above. Studies of interest would dertaken by Pickstone et al. (2009). The search strategy
include children with SSD aged between 2 and 6 years; described below outlines the larger review carried out for
use a range of study designs; and measure outcomes the Child Talk research programme and describes how
in speech. The intention was that this would provide the studies relevant to SSD were identified within this.
an overview of current evidence for intervention for The systematic review was registered with PROSPERO
SSD with preschool children in an easily accessible for- (registration number CRD42013006369), an interna-
mat which could be quickly be mapped onto individual tional register of prospective systematic reviews.
children’s needs.
This study was part of a larger review of interven-
tions for children with speech and language impairment Search strategy
in preschool children with no concomitant difficulties The search strategy employed three key elements:
(Roulstone et al. 2015) within the ‘Child Talk’ research (1) the development of a comprehensive and relevant
programme, a series of research studies investigating the list of search terms to ensure that all potentially valid
evidence base for speech and language therapy interven- studies in relation to interventions for speech and lan-
tion for preschool children. guage impairment without concomitant difficulties were
returned; (2) the exploration of a suitably broad range
of databases to capture as many potentially valid stud-
Method
ies as possible, including published, unpublished and
The systematic review was guided by the principles conference proceedings; and (3) the identification of
outlined in the Cochrane Collaboration methodology clear inclusion criteria against which to filter potentially
(Higgins and Green 2011), as far as they could be applied valid studies and provide the dataset for analysis. The
450 Yvonne Wren et al.
authors and co-applicants of the Child Talk programme Search procedure
of research (Roulstone et al. 2015) identified a set of
A combination of ‘free text’ terms with Boolean opera-
search terms based on their previous work in the field
tors and truncations was used. Eighteen separate searches
(Blackwell et al. 2014, Hambly et al. 2013, Marshall
were conducted in electronic databases (see appendix B)
et al. 2011, Pickstone et al. 2009, Wren et al. 2013).
to identify appropriate studies in papers published from
Further potential search terms were identified from
the earliest entries of any of the databases until January
key papers. This expertise was augmented by consul-
2012. Papers were initially reviewed by title and then by
tation with information specialists. Through an itera-
abstract.
tive process of identification and discussion, a list of 90
search terms was determined to provide the most ap-
propriate set to capture potentially valid studies (see Reliability
appendix A). The same process was used to select
appropriate databases to ensure maximum inclusion Two of the authors independently reviewed the titles of
of published data, unpublished data and conference 10% of the papers identified from the initial search of
proceedings. the databases to screen for relevance, removing any stud-
In line with Booth and Fry-Smith (2003), the ies that did not fit the exclusion and inclusion criteria.
PICO model (population, intervention, comparison, There was 100% consensus and the remaining 33,000
outcome) guided the development of the inclusion crite- references were shared between these two authors and
ria. All research design methodologies were considered papers were excluded at the title level. This process lead
and therefore the ‘comparison’ element of the PICO to the retention of 4574 papers. The abstract review
model was not used to determine eligibility, but recorded was undertaken by four members of the research team,
during data extraction. For inclusion in the larger with two people for each manuscript (one speech and
Child Talk review, studies had to meet the following language therapist and one psychologist). Where dis-
requirements: agreements occurred, discussion took place within the
team until consensus was reached. Those papers retained
r Population: at least 80% of the sample was re- at this stage were then reviewed in their entirety in light
quired to be within the age range 2;00–5;11 at the of the inclusion and exclusion criteria.
start of the intervention or at recruitment; chil- The retained papers were further reduced to those
dren would be diagnosed or considered ‘at risk’ that had interventions which related to SSD. Studies
of speech and language impairment without con- were included at this stage if the intervention described
comitant difficulties. in the research was consistent with the definition: ‘Work
r Intervention: an empirical evaluation of an in- that increases the accuracy of speech production or ar-
tervention, including randomized controlled tri- ticulation, often focusing on specific sound(s).’ Those
als, experimental and quasi-experimental stud- studies that focused on phonological awareness skills
ies and case studies, which included multiple only and did not relate to speech output were excluded.
baseline or other systematic manipulation of the The remaining papers were then subjected to a quality
intervention. appraisal.
r Outcomes: at least one of the primary out-
come measures of included studies would address Quality appraisal
speech, language, communication or interaction;
at a later stage, those studies that included primary The quality appraisal tools used in this review were se-
outcome measures of speech were included in this lected to be relevant to the research designs used in the
topic specific review (see below). included studies. Two tools were used for this purpose:
(1) the Physiotherapy Evidence Database quality assess-
Studies were excluded if: ment tool (PEDro-P; Perdices and Tate 2009) had a
score range of 0–9 and was used to appraise the method-
ological quality of randomized and non-randomized
r they related to children whose speech or language controlled trials; and (2) single-case experimental de-
appeared to be developing typically with no evi- sign (SCED) had a score range of 0–10 and was used for
dence to suggest that their language was ‘at risk’; single case studies (Tate et al. 2008). All appraisers un-
r they related to children whose speech or language dertook and passed training on PEDro-P and SCED.1
delays were associated with other developmental Each paper was reviewed by at least two researchers, and
or pervasive conditions such as learning difficul- if disagreement had occurred, it was planned to discuss
ties, autism, cleft palate and cerebral palsy; and/or and reach consensus. This process was not required as
r the only outcomes were social or behavioural. agreement on the quality assessment was 100%. For
Systematic review of speech interventions 451
Table 1. Process of categorization of procedures in intervention for speech-sound disorder (SSD)
Auditory Cognitive
Environmental perceptual linguistic Production Combined
Description Procedures Procedures that target Procedures that require the Procedures that aim to Procedures that
incorporated listening and perceptual child to reflect on their effect change through combine two or more
into everyday skills speech and/or increase instruction on of the other four
interactions their awareness of speech production and categories into a
generally production practice tested intervention
Examples Modelling, Auditory discrimination, Contrast therapy, Drills, guidance on Cycles approach,
recasting focused auditory metalinguistic tasks phonetic placement or psycholinguistic
stimulation, phoneme manner, traditional approach
perception tasks articulation
both tools, a higher score was associated with a greater Subsequently, effect sizes for speech outcomes were
quality of the methodology applied and reported within calculated where data were available and appropriate.
the study. In line with previous reviews (Camarinos and This was undertaken using the Campbell Collabora-
Marinko 2009, Maher et al. 2003), a score of 6 or over tion effect size calculator.2 Studies using a within-subject
was used to identify studies of acceptable quality which pre-post-methodology providing sufficient information
would be retained in the review. These studies were then were assessed using a second online calculation tool3 and
mapped onto the classification of intervention proce- single-subject experimental designs were assessed using
dures model described above. improvement rate difference (IRD; Parker et al. 2011).
Figure 2. Preferred Reporting Items for Systematic Reviews and Meta-Analyses (PRISMA) flow chart. [Colour figure can be viewed at
wileyonlinelibrary.com]
and a further four used a between-groups design. The each of the studies in the review and provides summary
26 studies were categorized according to the procedure information on each obtained from the data extraction.
used in the intervention using the model in figure 3. Environmental approaches are represented by one
It was possible to calculate effect sizes in 10 of the stud- study. Yoder et al. (2005) was categorized here due to
ies and to provide a range of the improvement rate the intervention using recasting and modelling within
difference in single cases for three more. Table 2 details clinic contexts. This study found no main effect of the
Systematic review of speech interventions 453
1
Environmental Auditory Perceptual Cognive-Linguisc Producon Integrated Approaches
2
Combined
Phoneme Focused Oro-motor Guidance on Imitaon & Drill approaches Unspecified
Meaningful Complexity Meta-
Percepon Auditory Speech Phonec
Minimal approaches linguisc
Smulaon exercise Placement/
Contrast Includes
Manner
(phonological
awareness) Glogowska et al.2000
Yoder et al. 2005 Baker and McLeod 2004 Forrest and Elbert 2001
Rvachew 1994 Dodd and Iacono 1989 Forrest et al. 2000 Almost and Rosenbaum 1998
Rvachew et al. 2004 Robb et al. 1999 Gierut 1989 Gierut 1996 Hart and Gonzalez 2010
Wolfe et al. 2003 Gierut 1990 Gierut and Champion 2000 McIntosh and Dodd 2008
Gierut and Champion 1999 Gierut and Champion 2001 Saben and Ingham 1991
Gierut et al. 1996 (both studies) Gierut and Morrisee 1996
Rvachew and Nowak 2001 Winner and Elbert 1988
1 = Includes modelling and recasng and other approaches which are embedded in everyday interacons
2 = Imitaon /spontaneous producon of sounds in a progressively more complex context - syllables, words or non-words
Figure 3. Evidence for intervention procedures for preschool children with speech-sound disorder (SSD). [Colour figure can be viewed at
wileyonlinelibrary.com]
broad target recast intervention but did report a posi- No studies were included in the review under the cate-
tive long-term impact on intelligibility for children with gory of metalinguistic approaches.
low pretreatment speech accuracy in comparison with Studies within the review that came under the cat-
standard care. egory of production were identified within the subcate-
Within the category of auditory perceptual ap- gories of ‘oro-motor speech exercises’, ‘guidance on pho-
proaches, the subcategory of phoneme perception ap- netic placement/manner’ and ‘imitations and drill’. No
proaches was used in three studies (Rvachew 1994, studies were categorized under ‘oro-motor speech ex-
Rvachew et al. 2004, Wolfe et al. 2003). The children ercises’ or ‘guidance on phonetic placement/manner’.
in Rvachew (1994) were randomly allocated to three The seven studies within the ‘imitations and drill’ sub-
groups and these children were given listening tasks fo- category all worked on increasing the complexity of ar-
cused on treatment of misarticulated versions of target ticulation in graded steps such as breaking words into
words. Rvachew et al. (2004) used training in phone- constituent sounds and subsequently recombining to
mic perception, letter recognition, letter–sound associ- form the word (Forrest and Elbert 2001, Forrest et al.
ation and onset-rime matching. Both studies found a 2000, Gierut 1996, Gierut and Champion 1999, 2001,
positive effect of the intervention. In contrast, Wolfe Gierut and Morrisette 1996, Winner and Elbert 1988).
et al. (2003) compared sound identification training Five of these studies showed an improvement in the in-
plus production training with production-only train- tervention group (Forrest and Elbert 2001, Forrest et al.
ing and found no difference between the two groups 2000, Gierut and Champion 2000, 2001, Gierut and
except for sounds which were poorly identified prior Morrisette 1996), while in two studies there was no sta-
to intervention. None of the studies in the review tistical impact of the intervention on the child’s speech
was classified under the focused auditory stimulation output (Gierut 1996, Winner and Elbert 1988). It is
subcategory. important to note, however, that the purpose of the in-
Cognitive–linguistic approaches were the most com- tervention Winner and Elbert (1988) was to investigate
monly reported interventions within the studies in the the impact of administering repeated probes during in-
review. These studies focused on three subcategories of tervention with the intention that a desired outcome
intervention: ‘meaningful minimal contrast’ approaches, would be no change in performance on the probe mea-
‘complexity’ approaches and ‘metalinguistic approaches’. sure, indicating that this approach can continue to be
Three studies focused on meaningful minimal contrast used in future trials of intervention for SSD.
(Baker and McLeod 2004, Dodd and Iacono 1989, ‘Integrated’ approaches to intervention were repre-
Robb et al. 1999) and a further six studies (from five sented by studies within the subcategories of ‘combined’
papers) form the evidence base for (Gierut 1989, 1990, approaches and ‘unspecified’. Combined approaches
Gierut and Champion 1999, Gierut et al. 1996) and were adopted in four studies included in the review
against (Rvachew and Nowak 2001) complexity ap- (Almost and Rosenbaum 1998, Hart and Gonzalez
proaches. These studies have small samples but suggest 2010, McIntosh and Dodd 2008, Saben and Ingham
a positive impact of the interventions on the children, 1991). They used a combination of activities and strate-
with one exception where change to the target of inter- gies as interventions, described as being targeted at the
vention was not observed (Gierut and Champion 1999). individual child’s needs or as routine one-to-one therapy.
454
Table 2. Summary of studies from the systematic review
Number of child
participants (number No. of therapy Effect size Cohen d
Reference and of children in each Age range Study design (type of sessions/agent of Length of each Frequency of Duration of type of speech Analysis used to PEDro-P/SCED unless otherwise
country of origin group, if applicable) (months) evidencea ) delivery session (min) sessions intervention sampled measure change score specified
Environmental
Yoder et al. 52 (26, 26) Group 1: Randomized (type II) Group 1: control 0; 30 min Three times per 6 months Spontaneous Percentage intelligible PEDro-P 7 49 (taken directly
(2005), USA average 44.3 Group 2 week speech utterance from the paper)
Group 2: (treatment PVCb
average 43.2 group) 72/SLP PCCb
Rvachew et al. 34 (17, 17) Group 1: Randomized (type II) 16 (in addition to 15 min Weekly 4.73 months Conversation PCCb PEDro-P 6 0.8316
(2004), average 52.88 their regular
Canada Group 2: therapy)/SLP
average 50.29
Wolfe et al. 9 (4, 5) Group 1: Comparative Average 30 min Twice weekly One academic Probe list Accuracy of PEDro-P 6 –0.3634
(2003), USA 47–55 studies— 11/SLP quarter production
Group 2: randomized Sound identification
41–50 therapy approach
(type II)
Cognitive–linguistic: meaningful minimal contrast
Baker and 2 Subject 1: 57 Single-subject 1–12 45 min Twice weekly 1–6 weeks Probe Percentage correct SCED 7 0.001c
McLeod Subject 2: 52 studies—case 2–32/SLP 2–16 weeks conversation production of
(2004), report, A–B, trained cluster
Australia multiple baseline
design (type IV)
Dodd and Iacono 7 36–57 Case series pre-post- 3–40/SLP n.a. Weekly Average 23.6 Spontaneous PCCb SCED 6 –1.362c
(1989), intervention weeks speech (during Phoneme inventory
Australia design (type IV) play) Process analysis
RIUb
Robb et al. 1 48 Case study: single 20/SLP 45 min Twice weekly 10 weeks Speech sample Percentage accuracy SCED 6 Insufficient data
(1999), USA subject pre-post- Probe list Vowel inventory
intervention PVCb
design (type IV) Acoustic analyses of
vowels (duration,
fundamental
frequency)
Continued
Yvonne Wren et al.
Table 2. Continued
Number of child
participants (number No. of therapy Effect size Cohen d
Reference and of children in each Age range Study design (type of sessions/agent of Length of each Frequency of Duration of type of speech Analysis used to PEDro-P/SCED unless otherwise
country of origin group, if applicable) (months) evidencea ) delivery session (min) sessions intervention sampled measure change score specified
Continued
455
456
Table 2. Continued
Number of child
participants (number No. of therapy Effect size Cohen d
Reference and of children in each Age range Study design (type of sessions/agent of Length of each Frequency of Duration of type of speech Analysis used to PEDro-P/SCED unless otherwise
country of origin group, if applicable) (months) evidencea ) delivery session (min) sessions intervention sampled measure change score specified
Gierut and 8 40–75 Single-subject n.a./SLP 60 min Three times per n.a. Probe list Percentage accuracy SCED 9 IRDd —between
Champion studies—multiple week correct on probe list 84% and 100%
(2001), USA baseline design
(type III-2)
Gierut and 2 47–62 Single-subject n.a./SLP 60 min Three times per Average of 16 Probes Phoneme inventory SCED 6 Insufficient data
Morrisette studies—multiple week weeks
(1996), USA baseline design
(type III-2)
Winner and 4 46–68 Single-subject 25/SLP 30 min Three times per 8 weeks Speech sample Percentage correct SCED 7 IRDd —between
Elbert (1988), studies—multiple week Probe list scores of target 50% and 100%
USA baseline design Spontaneous sounds
(type III-2) speech (picture
description)
Integrated approaches: combined
Almost and 26 (13, 13) 33–61 Group studies— 14–29/SLP 30 min Twice weekly 7–15 weeks GFTAb Single words PEDro-P 9 0.0004
Rosenbaum randomized (type APP-Rb Number of errors
(1998), II) Standardized test PCCb
Canada of single words
Conversational
speech
Hart and 3 43–59 Single-subject 12/SLP 30 min Twice a week 6 weeks HAPP-R 3b Process analysis SCED 8 IRDd —between
Gonzalez studies—multiple Spontaneous Percentage sample 0% and 100%
(2010), USA baseline design speech sample correct
(type III-2)
McIntosh and 3 36–45 Single-subject pre- Between 12 and 30–40 min Twice weekly Between 6 and Single word PVCb SCED 6 –42.187c
Dodd (2008), post-intervention 38/SLP 19 weeks naming test PCCb
Australia design (type IV) (average (DEAPb PPCb
12.8 weeks) phonology Percentage
subtest) inconsistency
Connected
speech task
(DEAPb )
Repeated
production of
words
(DEAPb —
inconsistency
subtest)
Continued
Yvonne Wren et al.
Systematic review of speech interventions 457
The studies provide mixed evidence for this approach:
APP-R = Assessment of Phonological Processes—Revised (Hodson 1986); DEAP = Diagnostic Evaluation of Articulation and Phonology (Dodd et al. 2002); GFTA = Goldman–Fristoe Test of Articulation (Goldman and Fristoe 1969, 2000);
HAPP-R = Assessment of Phonological Processes—Revised (Hodson 2004); PCC = per cent consonants correct; PPC = per cent phonemes correct; PVC = percentage vowels correct (Shriberg and Kwiatkowski 1982); PPKP = productive
Effect size Cohen d
unless otherwise
Insufficient data
Almost and Rosenbaum (1998) showed a positive ef-
specified
fect of active therapy in a group study while the re-
0.0477
maining three studies reported case studies with varying
patterns of response from individuals. Unspecified ap-
PEDro-P/SCED
PEDro-P 8
SCED 8
Percentage use of
phonological knowledge profile (Gierut et al. 1987); Psycholinguistic Framework (Stackhouse and Wells 1997); RIU = relative influence on unintelligibility (Dodd and Iacono 1989).
Delivery of intervention
type of speech
(spontaneous
Notes: a National Health and Medical Research Council (NHMRC) (2007) evidence hierarchy: designations of ‘levels of evidence’ according to the type of research question.
naming)
picture
Probe list
8.4 months
intervention
Duration of
Effect size was calculated using a within-subject design and online calculator from http://www.cognitiveflexibility.org/effectsize/effectsizecalculator.php/.
Average of
30 and 60 min.
Once a month
IRD = improvement rate difference, a method of calculating the effect size for single-subject experimental designs (Parker et al. 2011).
sessions
Table 2. Continued
6.2 h/SLP
Average
therapy approach
baseline design
randomized
(type III-2)
Single-subject
Comparative
(type II)
Group 2:
18–42
24–42
group, if applicable)
of children in each
Number of child
Glogowska et al.
(2000), UK
Reference and
c
458 Yvonne Wren et al.
included process analysis (Assessment of Phonologi- evidence forward. As a counter to the inclusion of studies
cal Processes—Revised; Hodson 1986, 2004), phone- with lower-graded evidence, the quality appraisal tools
mic or phonetic inventories (Productive Phonological were used to identify studies with the most robust oper-
Knowledge Profile; Gierut et al. 1987), percentage ationalizations of these designs and reporting processes.
phonemes/consonants/vowels correct (Diagnostic Eval- It should be noted, however, that where higher-
uation of Articulation and Phonology; Dodd et al. graded study designs were used, results could shed a fur-
2002, Shriberg and Kwiatkowski 1982), and accuracy ther light on lower-graded designs. For example, whereas
of production (Goldman–Fristoe Test of Articulation; the studies by Gierut (1989, 1990, 1996) showed a pos-
Goldman and Fristoe 2000). Where spontaneous speech itive outcome for the complexity approach in single case
samples, confrontation picture naming or probe lists designs, Rvachew and Nowak (2001) found that greater
were used, a number of analyses were carried out, as change was observed in children who received input
detailed in table 2. following a developmental rather than a complexity ap-
proach to intervention in a higher-graded group study.
Similarly, the group study carried out by Almost and
Discussion
Rosenbaum (1998) provides more convincing evidence
This systematic review of the literature has considered for their combined approach to intervention in compar-
the evidence for a range of interventions for preschool ison with the case studies reported by others within this
children with SSD within a model in which interven- category of interventions.
tions were classified based on the nature of the proce- The data-extraction process revealed that many stud-
dures used to effect change. In total, 55 papers were ies did not report complete data regarding dosage, but
identified based on clearly defined search criteria. Fol- where these were reported, there was a wide range in the
lowing quality appraisal, 25 papers reporting 26 studies number of sessions provided (3–67). However, there
were appraised as robust enough to be included in the were no clear patterns to the dosage provided within the
final review. These 26 studies were then mapped onto categories and subcategories of interventions. Rather,
the model of interventions according to the description where it was reported, a wide range of number, frequency
of the procedures within each paper. and duration of intervention sessions were offered. Lack
of consistency in the provision of intervention makes it
harder to compare across interventions and to determine
Description of the review
the relative benefit of each.
While some previous reviews have limited their enquiry With regards to measuring outcomes, a range of tools
to children with phonological problems only (Baker and were used to assess speech output including published
McLeod 2011), this review included any study that tar- assessments, picture-naming tasks and spontaneous con-
geted increased accuracy of speech production or ar- tinuous speech samples. As with dosage, there were no
ticulation, encompassing both phonological and speech clear patterns within the categories and subcategories
motor interventions. This was important given the aim with regard to outcome data collection and analysis.
of synthesizing the evidence for clinicians who will be Thus, a narrative synthesis has been used rather than
faced with a broad spectrum of children with SSD in an attempt made at a meta-analysis where the measures
practice (Broomfield and Dodd 2004, Shriberg et al. differed widely. The exception to this was the subcate-
2005). gories of imitation and drill and complexity approaches
The review included a range of research designs which both relied heavily on probe word lists to test
and did not limit itself to randomized control trials, outcomes. However, these studies were predominantly
though most were at level III of the NHMRC Evidence carried out by two groups of researchers, which may ex-
Hierarchy (NHMRC 2007) and, therefore, were ei- plain the tendency towards the same measurement tools
ther pseudo-randomized controlled trials or compara- rather than indicating consensus across research groups
tive studies with or without concurrent controls. Pre- in favour of any particular measure.
vious reviews (Law et al. 2003, Lee and Gibbon 2015,
Morgan and Vogel 2008) have followed more restrictive The model for classifications of interventions
criteria with regards to study design. However, in order
for SSD
to reflect the growing evidence base and the potential for
lower-graded studies to develop into larger studies with The classification model used to classify those inter-
more robust research designs, the decision was made to ventions included in the review was developed us-
include studies with a lower level of evidence, as defined ing a bottom-up approach based on interventions de-
by the NHMRC (2007). This allowed an investigation scribed by clinicians in practice (Roulstone and Wren
of the current level of evidence for interventions and 2001). The model proposes five main categories (en-
a clear picture regarding what is required to take the vironmental, auditory–perceptual, cognitive–linguistic,
Systematic review of speech interventions 459
production and integrated) that distinguish interven- supported by a number of good-quality studies, but
tions according to where change, which will lead to im- the level of evidence represented in each of these studies
proved speech output, is expected to occur. The subcat- is low based on the NHMRC (2007) classification of
egories attempt to capture more precisely what is being levels of evidence. Across these three subcategories of
asked of the child in order to effect change. An exhaus- intervention procedure, the highest graded study was at
tive list of possibilities is not presented, however, and level III-2: a comparative study with concurrent con-
the model will undoubtedly evolve as new intervention trols. This is comparable with a classification of indica-
procedures emerge and the evidence base grows. tive evidence based on the ‘What Works’ database of
interventions (Law et al. 2015). The fact that there are
studies with higher-grade evidence adds credence to the
Mapping the evidence to the model
findings for the category or subcategory as a whole, but
Categorization of studies to the model was complex. there is still a need for more studies using a higher level
Many of the studies included could have been cate- of evidence methodologies to strengthen the evidence
gorized under the subcategory of ‘combined’, e.g., all base for these types of intervention. This fits with the
three of the studies listed under auditory perceptual findings of Baker and McLeod (2011) who commented
included production activities. However, studies were on the need for higher levels of scientific rigour and
categorized according to the specific element of the in- the importance of replication research to build on the
tervention being investigated. Some studies added com- findings of lower-graded studies.
ponents to their interventions during the course of their Higher-grade evidence was identified in the re-
study making it difficult to assess the particular contribu- view for three studies: one using phoneme percep-
tion to outcome relative to the original aim of the study tion (Rvachew et al. 2004), one that used a com-
(McIntosh and Dodd 2008, Saben and Ingham 1991). bined approach (Almost and Rosenbaum 1998); and a
Further difficulties arose concerning the amount of in- third where the intervention procedure was unspecified
formation regarding intervention procedures provided (Glogowska et al. 2000). All three studies were random-
in the paper. With more information, it is possible that ized controlled trials with large sample sizes relative to
some of the studies reported would be re-categorized most of the other studies (34, 26 and 26 respectively).
into a different group. Given that a range of interventions was used within these
The majority of studies in the review focused on studies, this suggests there is agreement that a variety of
just three of the 11 subcategories of the model: imi- approaches to intervention can be effective for children
tations and drill (seven studies), meaningful minimal with SSD (Lancaster et al. 2010).
contrasts (three studies) and complexity (six studies).
The remaining studies covered a further four cate-
Clinical implications
gories/subcategories. Thus, no studies were identified
for four of the subcategories of the model. It is possible The review and categorization of the studies onto the
that no evidence is available for each of these subcate- model of interventions, as illustrated in figure 3, pro-
gories or that the evidence that is available was not robust vides an easy reference for clinicians regarding which
enough to be included in the review, despite the broader interventions have evidence to support them. The cate-
inclusion criteria of this review compared with others. gories of intervention can also be mapped onto the needs
Rather than suggesting that those subcategories with no of individual children. For example, where assessment
studies in the review are ineffective, the more accurate has shown that a child’s presenting SSD is associated
conclusion would be that currently there is no strong with problems in auditory processing, the interventions
evidence to support these intervention procedures with described by Wolfe et al. (2003) and Rvachew (1994)
preschool-aged children. and Rvachew et al. (2004) could be useful. The de-
Some degree of supporting evidence was identified scriptions in the individual papers regarding both the
for seven of the intervention categories and subcate- activities carried out and the manner of delivery, in
gories in the model. These covered all the five main terms of number and frequency of sessions, can assist
categories and a range of subcategories: environmen- in providing information for an evidence-based service.
tal approaches; phoneme perception; guidance on pho- Similarly, if assessment reveals that a child’s needs appear
netic placement/manner; imitations and drill; contrasts; to be in the areas of cognitive–linguistic processing or
complexity; combined and unspecified approaches. The production skill, the relevant studies in each category
number of quality studies varied across these subcat- can be used to guide the plan for intervention. Though
egories, from just one each for ‘environmental’ and more comparative studies need to be completed to deter-
‘guidance on phonetic placement/manner’ to seven for mine the degree to which some approaches are more ef-
imitation and drill. Three subcategories in the model, fective or efficient than others within categories, the abil-
imitations and drill, contrasts and complexity, were ity to identify specific approaches mapped to children
460 Yvonne Wren et al.
with specific needs is invaluable in the clinical context higher-graded methodological studies which will pro-
when time for considering the literature to cover a broad vide more robust information on which approaches or
range of presentations for SSD is limited. combination of approaches are most suitable to use with
this client group.
Strengths and limitations of the study
Acknowledgements
The systematic review had a specific remit to look at
the evidence base related to intervention for SSD with ‘Child Talk’—What Works presents independent research commis-
sioned by the National Institute for Health Research (NIHR) under
preschool children (2;00–5;11). Studies with 20% or its Programme Grants for Applied Research funding scheme (grant
more of children outside the specified age range were number RP-PG-0109-10073). The views expressed here are those of
not included. The criteria for inclusion meant that some the authors and not necessarily those of the National Health Service
frequently cited papers were not included in the review. (NHS), the NIHR or the Department of Health. Child Talk was
The reasons for non-inclusion were most often related a large programme and we are indebted to our co-applicants and
members of the team for their wisdom, support and input to the
to the age range of the children in the sample or a low programme as a whole, and to their influence on all outputs from
score on the quality appraisal tools used. Some stud- the programme: Lydia Morgan, Naomi Parker, Rebecca Coad, Julie
ies were also excluded because the sample used in the Marshall, Linda Lascelles, Jane Coad, Norma Daykin, Alan Emond,
study included children with known concomitant dif- Jenny Moultrie, Tim Peters, Jon Pollock, Jane Powell, Cres Fernandes
ficulties such as cleft palate or hearing loss or because and William Hollingworth. Declaration of interest: The authors re-
port no conflicts of interest. The authors alone are responsible for
outcomes were not reported for speech (see appendices C the content and writing of the paper.
and D for excluded studies). Moreover, as the outcome
measure needed to include speech output, the review
did not include interventions that focused on prosodic Notes
skills or speech perception or other underlying speech 1. See http://speechbite.com/rating-research-quality/outline-rating-
processing skills unless these were included alongside a training-program/.
measurement of speech output. 2. See https://www.campbellcollaboration.org/escalc/html/Effect
SizeCalculator-SMD-main.php/.
3. See http://www.cognitiveflexibility.org/effectsize/.
Conclusions 4. See http://www.prisma-statement.org (accessed on 3 March
2016).
To summarize, there is evidence to support certain types
of intervention for preschool children with SSD and References
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Systematic review of speech interventions 463
WREN, Y., 2005, An evaluation of the use of computers in phonology 36. Language Development/
therapy. Unpublished PhD thesis. 37. exp Nonverbal Communication/
WREN, Y., HAMBLY, H. and ROULSTONE, S., 2013, A review of 38. Communication Disorders/
the impact of bilingualism on the development of phonemic
awareness skills in children with typical speech development. 39. maternal responsiveness.tw.
Child Language Teaching and Therapy, 29, 11–25. 40. directiveness.tw.
YODER, P., CAMARATA, S. and GARDNER, E., 2005, Treatment effects 41. maternal interactive styles.tw.
on speech intelligibility and length of utterance in children 42. compliance.tw.
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44. child temperament.tw.
45. or/13-44
Appendix A: Search terms used in a systematic 46. exp Mental Retardation/
47. exp child development disorders, pervasive/or as-
review of interventions for speech-sound
perger syndrome/
disorder (SSD) in preschool children 48. Cleft Palate/or Cleft Lip/
1. exp Pediatrics/ 49. Otitis Media with Effusion/
2. exp CHILD/ 50. exp Hearing Loss/
3. exp INFANT/ 51. exp Blindness/
4. child$.mp. [mp = title, original title, abstract, name 52. Stuttering/
of substance word, subject heading word] 53. Aphonia/
5. infant$.mp. [mp = title, original title, abstract, 54. exp Pain/
name of substance word, subject heading word] 55. Crying/
6. (paediatric$ or pediatric$).mp. [mp = title, origi- 56. exp Analgesia/
nal title, abstract, name of substance word, subject 57. Reading/
heading word] 58. exp Dyslexia/
7. toddler$.mp. [mp = title, original title, abstract, 59. Cerebral Palsy/
name of substance word, subject heading word] 60. (alternative and augmentative communication).mp.
8. boy$.ti,ab. [mp = title, original title, abstract, name of sub-
9. girl$.ti,ab. stance word, subject heading word]
10. (school child$ or schoolchildren$).ti,ab. 61. ‘alternative and augmentative communication’.mp.
11. (pre school$ or preschool$).ti,ab. [mp = title, original title, abstract, name of sub-
12. or/1-11 stance word, subject heading word]
13. speech disorder$.ti,ab. 62. exp aged/
14. speech intelligibility$.ti,ab. 63. geriatrics/
15. speech therap$.ti,ab. 64. or/46-63
16. language therap$.ti,ab. 65. (12 and 45) not 64
17. speech development.ti,ab. 66. randomized controlled trial.pt.
18. speech delay.ti,ab. 67. controlled clinical trial.pt.
19. language disorder$.ti,ab. 68. randomized controlled trials/
20. language development disorder$.ti,ab. 69. random allocation/
21. sign language$.ti,ab. 70. double blind method/
22. child$ language.ti,ab. 71. single blind method/
23. language therap$.ti,ab. 72. clinical trial.pt.
24. language development.ti,ab. 73. exp clinical trials/
25. language delay.ti,ab. 74. (clin$ adj25 trial$).tw.
26. nonverbal communication.ti,ab. 75. ((singl$ or doubl$ or trebl$ or tripl$) adj25 (blind$
27. non verbal communication.ti,ab. or mask$)).tw.
28. communication development.ti,ab. 76. placebos/
29. exp Speech Disorders/ 77. placebo$.tw.
30. speech Intelligibility/ 78. random$.tw.
31. ‘rehabilitation of speech and language disorders’/or 79. research design/
language therapy/or speech therapy/ 80. ‘comparative study’/
32. Language Development Disorders/ 81. exp evaluation studies/
33. Language Disorders/ 82. follow-up studies/
34. Sign Language/ 83. prospective studies/
35. Child Language/ 84. (control$ or prospectiv$ or volunteer$).tw.
464 Yvonne Wren et al.
85. (control$ or prospectiv$ or volunteer$).tw. 88. ‘human’/
86. or/66-85 89. 87 not 88
87. ‘animal’/ 90. 86 not 89
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466 Yvonne Wren et al.
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