Professional Documents
Culture Documents
22]
Case Report
ABSTRACT
Double lip is a rare dental anomaly affecting either upper or lower lip or concurrently. It may be congenital or acquired.
This deformity can affect the facial esthetics as it gets exaggerated while speaking, smiling, or chewing food. When it
interferes with speech, double lip may cause potential functional problems. The purpose of this article is to review the
literature on double lip and present a case series of maxillary double lip.
Key words: Ascher’s syndrome, counseling, double lip, macrochelia, oral anomaly, pars glabrosa, pars villosa, surgery
D
ouble lip is a rare oral anomaly affecting the Case 1
lips and is characterized by an excess mass of A 41-year-old healthy male patient reported to the
redundant mucosal tissue. The prevalence of Department of Oral Medicine and Radiology with a
double lip or “macrochelia” affecting the upper lip complaint of dirty teeth and bleeding gums for the last
is greater than that of lower lip.[1,2] Current incidence 3-4 months. The patient did not report any history of
of double lip is unknown, although Calnan stated in trauma, allergy, and/or medical problems. Clinical
1952 that there were only a dozen cases reported in examination revealed an extra fold of tissue originating
literature.[3] English reported its rate of occurrence as from the inner aspect of the upper lip [Figure 1], which
approximately 1 in 480 Chileans and 1 in 200 White was evident at rest but got accentuated when the patient
people in Utah.[4] Cases of double lip do occur in the smiled. The fold of excess tissue was separated by a mild
general population, but probably they are not well midline constriction [Figure 2]. A provisional diagnosis
documented in literature. Male predilection of 7:1 has of congenital bilateral maxillary double lip and chronic
been reported.[5] Double lip may occur in isolation or generalized periodontitis was made. As the patient
in association with Ascher’s syndrome, hemangioma, was unaware of this finding and denied any esthetic
bifid uvula, cleft palate, or cheilitis glandularis.[5-7] The
authors present a case series of maxillary double lip in This is an open access article distributed under the terms of the
Creative Commons Attribution-NonCommercial-ShareAlike 3.0
this article.
License, which allows others to remix, tweak, and build upon the
Access this article online work non-commercially, as long as the author is credited and the
new creations are licensed under the identical terms.
Quick Response Code:
Website: For reprints contact: reprints@medknow.com
www.jiaomr.in
DOI: How to cite this article: Desai VD, Das S, Kumar SM, Sadhwani H.
10.4103/0972-1363.170173
Maxillary double lip: A case series with review of literature.
J Indian Acad Oral Med Radiol 2015;27:314-7.
Address for correspondence: Dr. Vela D Desai, B-4O6, Trimurthy Apartment, Opposite BSNL Telecom Colony, Malviya Nagar,
Jaipur - 302 017, Rajasthan, India. E-mail: veladesai@hotmail.com
Received: 27-01-2015 Accepted: 19-10-2015 Published: 21-11-2015
314 © 2015 Journal of Indian Academy of Oral Medicine and Radiology | Published by Wolters Kluwer - Medknow
[Downloaded free from http://www.jiaomr.in on Saturday, April 20, 2019, IP: 103.5.132.22]
Figure 1: A fold of excess maxillary labial tissue Figure 2: Labial tissue approaching the cervical third of maxillary incisors
Journal of Indian Academy of Oral Medicine & Radiology | Apr-Jun 2015 | Vol 27 | Issue 2 315
[Downloaded free from http://www.jiaomr.in on Saturday, April 20, 2019, IP: 103.5.132.22]
Figure 3: Bilateral asymmetrical maxillary double lip Figure 4: Maxillary double lip- as the patient smiled. Also, missing teeth
replaced by implant (Healing abutment, second stage)
316 Journal of Indian Academy of Oral Medicine & Radiology | Apr-Jun 2015 | Vol 27 | Issue 2
[Downloaded free from http://www.jiaomr.in on Saturday, April 20, 2019, IP: 103.5.132.22]
Financial support and sponsorship 7. Cohen DM, Green JG, Diekmann SL. Concurrent anomalies:
Nil. Cheilitis glandularis and double lip. Report of a case. Oral Surg
Oral Med Oral Pathol 1988;66:397-9.
8. Rintala AE. Congenital double lip and Ascher syndrome: II.
Conflicts of interest
Relationship to the lower lip sinus syndrome. Br J Plast Surg
There are no conflicts of interest. 1981;34:31-4.
9. Lamster IB. Mucosal reduction for correction of a maxillary
References double lip. Report of a case. Oral Surg Oral Med Oral Pathol
1983;55:457-8.
1. Kenny KF, Hreha JP, Dent CD. Bilateral redundant mucosal tissue 10. Martins WD, Westphalen FH, Sandrin R, Campagnoli E.
of the upper lip. J Am Dent Assoc 1990;120;193-4. Congenital maxillary double upper lip: Review of the literature
2. Peterson A. Electrosurgical correction of maxillary double lip. and report of a case. J Can Dent Assoc 2004;70:466-8.
Den Dig 1972;78:182-8. 11. Parmar RC, Muranjan MN. A newly recognized syndrome with
3. Calnan J. Congenital double lip: Record of a case with a note on double upper and lower lip, hyperthelorism, eyelid ptosis,
the embryology. Br J Plast Surg 1952;5:197-202. blepharophimosis, and third finger clinodactyly. Am J Med Genet
A 2004;124A:200-1.
4. English GM. Embryology and anomalies of the mouth and
throat. Chapter 5. In: English GM, editor. Otolaryngology. 18th 12. Converse JM. Reconstructive Plastic Surgery. Vol. 3. Philadelphia:
ed. Philadelphia: JB Lippincott Company; 1988. p. 1-31. Saunders; 1977. p. 1543-4.
5. Palma MC, Taub DI. Recurrent double lip: Literature review and 13. Gomez-Duaso AJ, Seoane J, Vazquez-Garcia J, Arjona C. Ascher
report of a case. Oral Surg Oral Med Oral Pathol Oral Radiol syndrome: Report of two cases. J Oral Maxillofac Surg 1997;55:88-90.
Endod 2009;107:e20-3. 14. Oeak A, Cakur B. Double lip: A case report. J Dent App 2015;2:162-3.
6. Hanemann JA, Oliveira DT, Gomes MF, dos Anjos MJ, Sant’ana E. 15. Gadre PK, Agarwal R, Kumar S, Singh D, Chaudhary M. Maxillary
Congenital double lip associated to hemangiomas: Report of a double lip — A case report and review literature. Int J Res Health
case. Med Oral 2004;9:155-8. Sci 2014;2:871-4.
Journal of Indian Academy of Oral Medicine & Radiology | Apr-Jun 2015 | Vol 27 | Issue 2 317